摘要
Regional odontodysplasia (RO) is a rare, localized, nonhereditary developmental anomaly. The etiology of RO is currently unknown. The condition is more commonly found in females than males, and may affect both the primary and permanent dentitions in the maxilla and mandible. Diagnosis can be made based on the clinical, radiographic, and histopathologic findings. Clinically, the affected teeth show abnormal morphology and appear small, yellow, brown, and hypoplastic. Radiographically, the affected teeth show a ＂ghost-like＂ appearance with thin enamel and dentin, and large pulp chambers. Histopathological characteristics include hypoplastic and hypocalcified enamel, reduced dentin layer, and decreased quantity of tubules. In this report, we present a case of dental developmental anomaly in a 5-year-old female patient whose parents sought treatment with the chief complaint of ＂missing teeth.＂ Based on the clinical and radiographic features presented, we suspected the diagnosis of regional odontodysplasia involving both the primary and permanent incisors and canine on the left side of the anterior mandibular region. The conducted therapy was based on a conservative approach, in which the affected primary teeth were extracted, then processed for histopathological analysis. In view of these findings, we discuss the clinical, radiographic, and histopathological features of RO, as well as the diagnosis and treatment planning for RO.
並列摘要
局部牙齒發育不良是一種罕見且非遺傳性的發育異常，病因目前尚不清楚。好發率女性比男性常見，並會影響上顎和下顎的乳牙及恆牙發育。此種發育異常依據臨床表徵、影像學的檢查及組織病理切片的分析，就能進一步確診。在臨床表徵上，受影響的牙齒會出現異常的形態，大小會較一般牙齒小，顏色偏黃以及型態上發育不全等表徵。在影像學的檢查中，可以看到有較薄的牙釉質和牙本質，以及較大的牙髓腔，與一般的牙齒型態明顯不同，這種牙齒又稱為影子牙齒（ghost teeth）。在組織病理學中的特徵，包括發育不全和鈣化不全的牙釉質以及較少的牙本質層和牙本質小管。在本篇報告中我們提出了一位5歲女性患者的案例，主訴為缺牙。根據病人的臨床和影像學特徵，我們初步診斷為局部牙齒發育不良，其範圍包括下顎左側正中門牙、側門牙及犬齒。治療則是選擇較保守的方式，先將受影響的乳牙拔除進行組織病理學分析，進而診斷是否為局部牙齒發育不良。本篇文章會討論局部牙齒發育不良的臨床、放射學和組織病理學特徵，以及如何進行診斷和治療計劃。
延伸閱讀
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