Introduction: Myiasis is the infestation of live human and vertebrate animal with dipterous larvae which feed on the host's dead or living tissue. The most common anatomic sites for myiasis are the nose, eye, lung, ear, anus, vagina and more rarely, the mouth. Incidence of oral myiasis as compared to that of cutaneous myiasis is less as the oral tissues are not permanently exposed to the external environment. Case Report: A case of oral myiasis in the anterior maxillary region in a 12year- old male with mental retardation and cerebral palsy caused by the larvae (maggots) of Musca Nebulo (Family Diptera) (common housefly) is reported. The treatment consisted of manual removal of the larvae by topical application of turpentine oil (used for medicinal purpose) and surgical debridement of the oral wound. Conclusion: Preliminary measures taken to maintain good oral and general hygiene can prevent as well as treat myiasis.