A 76-year-old female patient complained blurred vision after receiving hydroxychloroquine (HCQ) 200mg twice a day for rheumatoid arthritis for two years. Slit-lamp examination showed whorl like pattern sub-epithelial brown deposits in bilateral cornea. Fundus examination revealed retinal pigment epithelium change around the macula in both eyes. HCQ was substituted by sulfasalazine for rheumatoid arthritis control. Vortex keratopathy alleviated three months after HCQ discontinuation; sub-epithelial deposits subsided six months after HCQ discontinuation. Best corrected visual acuity improved from 6/30 to 6/12.