Cutaneous fistulas may be an infection from dental origin such as dental caries, periodontal disease, and dental trauma, Delayed or ineffective treatment of cutaneous fistulas is often due to misdiagnosis and the absence of dental symptoms. This article describes a case of a ten-year-old girl with odontogenic cutaneous fistula. She was first diagnosed as an epidermal cyst and went through surgical removal under general anesthesia followed by debridement under local anesthesia. However, both of which failed to improve the symptom of fistula. She was transferred to dental department for evaluation. The source of infection was then re-diagnosed as dental pulp necrosis caused by dental caries in the mandibular right first molar. After being treated with root canal therapy in the first molar, the infected cutaneous fistula was recovered quickly within one month. The cutaneous lesion was completely healed at five months recall without any signs of recurrence. It is concluded that having correct diagnosis for these kinds of cases is important so that patients can avoid unnecessary surgical interventions.